ZNHIT6

Chr 1

zinc finger HIT-type containing 6

Also known as: BCD1, C1orf181, NY-BR-75

ZNHIT6 encodes a protein required for box C/D snoRNA accumulation and processing, snoRNA transport to the nucleolus, and ribosome biogenesis. Mutations cause autosomal recessive intellectual disability with delayed speech and language development. The gene shows no intolerance to loss-of-function variants based on population data.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
0
Pubs (1 yr)
14
P/LP submissions
0%
P/LP missense
1.16
LOEUF
Mechanism
Clinical SummaryZNHIT6
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
14 unique Pathogenic / Likely Pathogenic· 66 VUS of 105 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.16LOEUF
pLI 0.000
Z-score 0.93
OE 0.80 (0.561.16)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.30Z-score
OE missense 0.95 (0.851.05)
233 obs / 246.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.80 (0.561.16)
00.351.4
Missense OE0.95 (0.851.05)
00.61.4
Synonymous OE0.96
01.21.6
LoF obs/exp: 20 / 25.0Missense obs/exp: 233 / 246.1Syn Z: 0.27

ClinVar Variant Classifications

105 submitted variants in ClinVar

Classification Summary

Pathogenic12
Likely Pathogenic2
VUS66
Likely Benign7
12
Pathogenic
2
Likely Pathogenic
66
VUS
7
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
12
0
12
Likely Pathogenic
0
0
2
0
2
VUS
0
61
5
0
66
Likely Benign
0
5
2
0
7
Benign
0
0
0
0
0
Total06621087

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ZNHIT6 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found