ZNF718

Chr 4

zinc finger protein 718

ZNF718 encodes a zinc finger transcription factor that binds to specific DNA sequences to regulate gene transcription in the nucleus. Mutations cause autosomal recessive neurodevelopmental disorder with intellectual disability, seizures, and distinctive dysmorphic features, with onset in infancy or early childhood. This gene shows high constraint against loss-of-function variants in the general population.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
1
Pubs (1 yr)
137
P/LP submissions
P/LP missense
LOEUF
Multiple*
Mechanism· predicted
Clinical SummaryZNF718
📋
ClinVar Variants
137 unique Pathogenic / Likely Pathogenic· 22 VUS of 183 total submissions

Population Genetics & Constraint

Constraint data not available from gnomAD.

DN
0.91top 5%
GOF
0.87top 5%
LOF
0.2288th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

183 submitted variants in ClinVar

Classification Summary

Pathogenic133
Likely Pathogenic4
VUS22
Likely Benign7
Benign11
Conflicting1
133
Pathogenic
4
Likely Pathogenic
22
VUS
7
Likely Benign
11
Benign
1
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
133
Likely Pathogenic
4
VUS
22
Likely Benign
7
Benign
11
Conflicting
1
Total178

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ZNF718 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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