ZNF695

Chr 1

zinc finger protein 695

Also known as: SBZF3

The protein is predicted to function as a DNA-binding transcription factor that regulates gene expression by binding to specific DNA sequences and controlling RNA polymerase II-mediated transcription in the nucleus. Currently, no established human diseases have been definitively linked to mutations in this gene. The gene appears to be tolerant to loss-of-function variants based on constraint metrics, suggesting that complete loss of function may not cause severe developmental phenotypes.

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 1.85
Clinical SummaryZNF695
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
74 unique Pathogenic / Likely Pathogenic· 95 VUS of 177 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.85LOEUF
pLI 0.000
Z-score -0.16
OE 1.08 (0.551.85)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.17Z-score
OE missense 0.97 (0.871.08)
240 obs / 247.6 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE1.08 (0.551.85)
00.351.4
Missense OE0.97 (0.871.08)
00.61.4
Synonymous OE0.90
01.21.6
LoF obs/exp: 5 / 4.6Missense obs/exp: 240 / 247.6Syn Z: 0.77
DN
0.92top 5%
GOF
0.84top 5%
LOF
0.2289th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

177 submitted variants in ClinVar

Classification Summary

Pathogenic68
Likely Pathogenic6
VUS95
Likely Benign6
68
Pathogenic
6
Likely Pathogenic
95
VUS
6
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
68
0
68
Likely Pathogenic
0
0
6
0
6
VUS
0
77
18
0
95
Likely Benign
0
2
4
0
6
Benign
0
0
0
0
0
Total079960175

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ZNF695 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC