ZC3H3

Chr 8

zinc finger CCCH-type containing 3

Also known as: SMICL, ZC3HDC3

The protein is required for nuclear export of polyadenylated mRNAs and enhances SMAD-dependent transcription through ACVR1B signaling. Mutations in ZC3H3 cause neurodevelopmental disorders with intellectual disability, developmental delay, and various congenital anomalies, following an autosomal dominant inheritance pattern. The gene shows significant constraint against loss-of-function variants (LOEUF 0.41), reflecting its essential role in cellular RNA processing.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
2
Pubs (1 yr)
45
P/LP submissions
0%
P/LP missense
0.41
LOEUF
Mechanism
Clinical SummaryZC3H3
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.22) despite low pLI — interpret in context.
📋
ClinVar Variants
44 unique Pathogenic / Likely Pathogenic· 135 VUS of 200 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.41LOEUF
pLI 0.470
Z-score 4.10
OE 0.22 (0.120.41)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
-0.01Z-score
OE missense 1.00 (0.941.07)
592 obs / 591.6 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.22 (0.120.41)
00.351.4
Missense OE1.00 (0.941.07)
00.61.4
Synonymous OE1.23
01.21.6
LoF obs/exp: 7 / 32.1Missense obs/exp: 592 / 591.6Syn Z: -2.88

ClinVar Variant Classifications

200 submitted variants in ClinVar

Classification Summary

Pathogenic41
Likely Pathogenic3
VUS135
Likely Benign18
Benign2
Conflicting1
41
Pathogenic
3
Likely Pathogenic
135
VUS
18
Likely Benign
2
Benign
1
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
41
0
41
Likely Pathogenic
0
0
3
0
3
VUS
0
128
7
0
135
Likely Benign
0
15
0
3
18
Benign
0
1
1
0
2
Conflicting
1
Total0144523200

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ZC3H3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC