ZBTB14

Chr 18

zinc finger and BTB domain containing 14

Also known as: ZF5, ZFP-161, ZFP-5, ZFP161, ZNF478

ZBTB14 encodes a transcriptional regulator that activates the dopamine transporter gene and represses multiple genes including FMR1 and MYC by binding to specific DNA sequences in their promoters. Mutations cause autosomal recessive intellectual disability with speech delay, behavioral abnormalities, and developmental delays typically apparent in early childhood. The gene shows moderate constraint against loss-of-function variants (LOEUF 0.645), consistent with its recessive inheritance pattern.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
1
Pubs (1 yr)
122
P/LP submissions
0%
P/LP missense
0.65
LOEUF
Mechanism
Clinical SummaryZBTB14
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.25) despite low pLI — interpret in context.
📋
ClinVar Variants
117 unique Pathogenic / Likely Pathogenic· 43 VUS of 172 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.65LOEUF
pLI 0.261
Z-score 2.41
OE 0.25 (0.110.65)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
2.94Z-score
OE missense 0.48 (0.410.56)
123 obs / 255.2 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.25 (0.110.65)
00.351.4
Missense OE0.48 (0.410.56)
00.61.4
Synonymous OE1.06
01.21.6
LoF obs/exp: 3 / 12.0Missense obs/exp: 123 / 255.2Syn Z: -0.48

ClinVar Variant Classifications

172 submitted variants in ClinVar

Classification Summary

Pathogenic116
Likely Pathogenic1
VUS43
Likely Benign2
116
Pathogenic
1
Likely Pathogenic
43
VUS
2
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
116
0
116
Likely Pathogenic
0
0
1
0
1
VUS
0
36
7
0
43
Likely Benign
0
1
1
0
2
Benign
0
0
0
0
0
Total0371250162

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ZBTB14 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC