WNT5B

Chr 12

Wnt family member 5B

WNT5B encodes a secreted signaling protein that serves as a ligand for frizzled receptors and functions as a developmental signaling molecule affecting tissue regionalization over short distances. This gene is highly constrained against loss-of-function variants (LOEUF 0.494), suggesting mutations would likely cause severe developmental disorders, though specific associated phenotypes have not yet been clearly established in humans. The inheritance pattern for WNT5B-related disorders remains to be determined as clinical cases are identified.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
25
Pubs (1 yr)
65
P/LP submissions
0%
P/LP missense
0.49
LOEUF
Mechanism
Clinical SummaryWNT5B
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.59) — some intolerance to loss-of-function variants.
📋
ClinVar Variants
65 unique Pathogenic / Likely Pathogenic· 46 VUS of 121 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.49LOEUF
pLI 0.585
Z-score 2.97
OE 0.19 (0.090.49)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.79Z-score
OE missense 0.69 (0.610.78)
176 obs / 256.6 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.19 (0.090.49)
00.351.4
Missense OE0.69 (0.610.78)
00.61.4
Synonymous OE0.92
01.21.6
LoF obs/exp: 3 / 15.7Missense obs/exp: 176 / 256.6Syn Z: 0.69

ClinVar Variant Classifications

121 submitted variants in ClinVar

Classification Summary

Pathogenic62
Likely Pathogenic3
VUS46
Likely Benign6
62
Pathogenic
3
Likely Pathogenic
46
VUS
6
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
62
0
62
Likely Pathogenic
0
0
3
0
3
VUS
0
38
8
0
46
Likely Benign
0
4
0
2
6
Benign
0
0
0
0
0
Total042732117

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

WNT5B · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
WNT5B in Physiology and Disease
Suthon S et al.·Front Cell Dev Biol
2021
WNT5B in cellular signaling pathways.
Perkins RS et al.·Semin Cell Dev Biol
2022
Corrigendum: WNT5B in Physiology and Disease
Suthon S et al.·Front Cell Dev Biol
2021
Targeting WNT5B and WNT10B in osteosarcoma
Miranda-Carboni GA et al.·Oncotarget
2024
Top 5 full-text resultsSearch PubTator3 ↗