WDR12

Chr 2

WD repeat domain 12

Also known as: YTM1

WDR12 encodes a component of the PeBoW complex that is required for maturation of 28S and 5.8S ribosomal RNAs and formation of the 60S ribosome. Mutations cause Klippel-Feil syndrome 4 with neuropathy and developmental delay, which follows an autosomal recessive inheritance pattern. This gene is highly constrained against loss-of-function variants, indicating its critical role in cellular function.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 0.64
Clinical SummaryWDR12
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
28 unique Pathogenic / Likely Pathogenic· 56 VUS of 104 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.64LOEUF
pLI 0.000
Z-score 3.05
OE 0.38 (0.240.64)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.48Z-score
OE missense 0.91 (0.811.02)
199 obs / 218.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.38 (0.240.64)
00.351.4
Missense OE0.91 (0.811.02)
00.61.4
Synonymous OE0.94
01.21.6
LoF obs/exp: 11 / 28.6Missense obs/exp: 199 / 218.8Syn Z: 0.41

ClinVar Variant Classifications

104 submitted variants in ClinVar

Classification Summary

Pathogenic27
Likely Pathogenic1
VUS56
Likely Benign2
27
Pathogenic
1
Likely Pathogenic
56
VUS
2
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
27
0
27
Likely Pathogenic
0
0
1
0
1
VUS
0
52
4
0
56
Likely Benign
0
2
0
0
2
Benign
0
0
0
0
0
Total05432086

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

WDR12 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC