VBP1

Chr X

VHL binding protein 1

Also known as: HIBBJ46, PFD3, PFDN3, VBP-1

The encoded protein functions as a chaperone that binds to nascent polypeptide chains to promote proper protein folding and specifically transfers target proteins to cytosolic chaperonin, while also forming a complex with Von Hippel-Lindau protein and potentially facilitating its subcellular transport. Pathogenic variants in VBP1 cause X-linked intellectual disability with microcephaly through loss-of-function mechanisms. The high pLI score (0.88) and low LOEUF score (0.43) indicate strong intolerance to loss-of-function variants, consistent with X-linked inheritance.

Summary from RefSeq, UniProt
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0
Active trials
2
Pubs (1 yr)
0
P/LP submissions
P/LP missense
0.43
LOEUF
Mechanism
Clinical SummaryVBP1
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.88) — some intolerance to loss-of-function variants.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.43LOEUF
pLI 0.884
Z-score 2.46
OE 0.00 (0.000.43)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.36Z-score
OE missense 0.52 (0.390.69)
32 obs / 62.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.00 (0.000.43)
00.351.4
Missense OE0.52 (0.390.69)
00.61.4
Synonymous OE1.20
01.21.6
LoF obs/exp: 0 / 7.0Missense obs/exp: 32 / 62.1Syn Z: -0.77

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

VBP1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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