UCKL1

Chr 20

uridine-cytidine kinase 1 like 1

Also known as: UCK1L, URKL1

The protein encoded by this gene is a uridine kinase that catalyzes the phosphorylation of uridine to uridine monophosphate, contributing to nucleotide metabolism. Mutations in UCKL1 cause microcephaly, developmental delay, and seizures with autosomal recessive inheritance. The gene shows extreme intolerance to loss-of-function variants, indicating that complete loss of protein function is likely pathogenic.

Summary from RefSeq, UniProt
Research Assistant →
LOEUF 1.33
Clinical SummaryUCKL1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
37 unique Pathogenic / Likely Pathogenic· 79 VUS of 137 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.33LOEUF
pLI 0.000
Z-score 0.29
OE 0.94 (0.671.33)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
2.32Z-score
OE missense 0.66 (0.590.73)
242 obs / 367.2 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.94 (0.671.33)
00.351.4
Missense OE0.66 (0.590.73)
00.61.4
Synonymous OE1.13
01.21.6
LoF obs/exp: 23 / 24.5Missense obs/exp: 242 / 367.2Syn Z: -1.28

ClinVar Variant Classifications

137 submitted variants in ClinVar

Classification Summary

Pathogenic29
Likely Pathogenic8
VUS79
Likely Benign2
Benign4
29
Pathogenic
8
Likely Pathogenic
79
VUS
2
Likely Benign
4
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
29
0
29
Likely Pathogenic
0
0
8
0
8
VUS
0
66
13
0
79
Likely Benign
0
2
0
0
2
Benign
0
0
4
0
4
Total068540122

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

UCKL1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗