UBA6

Chr 4

ubiquitin like modifier activating enzyme 6

Also known as: E1-L2, MOP-4, UBE1L2

UBA6 encodes a ubiquitin-activating enzyme (E1) that initiates protein ubiquitination by adenylating and activating ubiquitin, and also activates the ubiquitin-like protein FAT10. Mutations cause autosomal recessive spastic paraplegia-81 and neurodevelopmental disorder with spastic paraplegia and microcephaly, presenting with developmental delay, intellectual disability, spastic paraplegia, and microcephaly. This gene is highly intolerant to loss-of-function variation (LOEUF 0.561) and is essential for embryonic development.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 0.56
Clinical SummaryUBA6
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.56LOEUF
pLI 0.000
Z-score 4.43
OE 0.40 (0.290.56)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.10Z-score
OE missense 0.87 (0.800.94)
461 obs / 532.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.40 (0.290.56)
00.351.4
Missense OE0.87 (0.800.94)
00.61.4
Synonymous OE0.94
01.21.6
LoF obs/exp: 26 / 64.3Missense obs/exp: 461 / 532.3Syn Z: 0.64

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

UBA6 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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