TVP23C

Chr 17

trans-golgi network vesicle protein 23 homolog C

Also known as: FAM18B2

The protein is predicted to function in protein secretion and vesicle-mediated transport at the Golgi membrane. Mutations in this gene have not been definitively associated with any recognized human disease or syndrome. The gene appears to tolerate loss-of-function variants well based on population genetic data.

ResearchSummary from RefSeq
MultiplemechanismLOEUF 1.43
Clinical SummaryTVP23C
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
118 unique Pathogenic / Likely Pathogenic· 5 VUS of 127 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.43LOEUF
pLI 0.000
Z-score 0.60
OE 0.80 (0.471.43)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.52Z-score
OE missense 1.12 (0.991.27)
167 obs / 149.0 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.80 (0.471.43)
00.351.4
Missense OE1.12 (0.991.27)
00.61.4
Synonymous OE1.00
01.21.6
LoF obs/exp: 8 / 10.1Missense obs/exp: 167 / 149.0Syn Z: 0.01
DN
0.6258th %ile
GOF
0.7030th %ile
LOF
0.3550th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

127 submitted variants in ClinVar

Classification Summary

Pathogenic115
Likely Pathogenic3
VUS5
Likely Benign3
115
Pathogenic
3
Likely Pathogenic
5
VUS
3
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
115
Likely Pathogenic
3
VUS
5
Likely Benign
3
Benign
0
Total126

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

TVP23C · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 2 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found