TTC4

Chr 1

tetratricopeptide repeat domain 4

Also known as: CNS1

The protein functions as a co-chaperone that recruits Hsp90 and Hsp70 molecular chaperones to nascent polypeptides, facilitating proper protein folding and supporting cellular translation through interaction with elongation factor eEF2. Mutations in TTC4 cause autosomal recessive intellectual disability with microcephaly, short stature, and facial dysmorphism. The gene shows tolerance to loss-of-function variants, consistent with the recessive inheritance pattern observed in affected individuals.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 0.90
Clinical SummaryTTC4
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.90LOEUF
pLI 0.000
Z-score 1.92
OE 0.55 (0.350.90)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.25Z-score
OE missense 0.95 (0.841.07)
188 obs / 198.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.55 (0.350.90)
00.351.4
Missense OE0.95 (0.841.07)
00.61.4
Synonymous OE0.92
01.21.6
LoF obs/exp: 12 / 21.7Missense obs/exp: 188 / 198.0Syn Z: 0.55
DN
0.78top 25%
GOF
0.6247th %ile
LOF
0.2092th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

TTC4 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →