TSNAX

Chr 1

translin associated factor X

Also known as: C3PO, TRAX

The protein acts as an endonuclease that combines with translin to activate the RNA-induced silencing complex (RISC) and facilitates nuclear transport of translin through its bipartite nuclear targeting sequences. Mutations cause autosomal recessive intellectual disability with developmental delay and seizures. This gene shows moderate constraint against loss-of-function variants (LOEUF 0.529), suggesting some intolerance to complete protein loss.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 0.53
Clinical SummaryTSNAX
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.20) despite low pLI — interpret in context.
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ClinVar Variants
38 unique Pathogenic / Likely Pathogenic· 32 VUS of 78 total submissions
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.53LOEUF
pLI 0.489
Z-score 2.82
OE 0.20 (0.090.53)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
1.30Z-score
OE missense 0.70 (0.600.82)
107 obs / 152.2 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.20 (0.090.53)
00.351.4
Missense OE0.70 (0.600.82)
00.61.4
Synonymous OE1.06
01.21.6
LoF obs/exp: 3 / 14.7Missense obs/exp: 107 / 152.2Syn Z: -0.33

ClinVar Variant Classifications

78 submitted variants in ClinVar

Classification Summary

Pathogenic35
Likely Pathogenic3
VUS32
Benign4
35
Pathogenic
3
Likely Pathogenic
32
VUS
4
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
35
0
35
Likely Pathogenic
0
0
3
0
3
VUS
0
28
4
0
32
Likely Benign
0
0
0
0
0
Benign
0
1
1
2
4
Total02943274

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

TSNAX · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
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