TRUB2

Chr 9

TruB pseudouridine synthase family member 2

The TRUB2 protein catalyzes pseudouridylation of mitochondrial mRNAs and tRNAs, and is required for mitochondrial ribosomal RNA abundance and intra-mitochondrial translation. The gene shows extreme intolerance to loss-of-function variants (pLI near 1.0), suggesting mutations would cause severe disease, but no specific clinical phenotype has been established yet.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 1.25
Clinical SummaryTRUB2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
Some data sources returned errors (1)

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Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.25LOEUF
pLI 0.000
Z-score 0.91
OE 0.73 (0.451.25)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.05Z-score
OE missense 0.99 (0.881.11)
209 obs / 210.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.73 (0.451.25)
00.351.4
Missense OE0.99 (0.881.11)
00.61.4
Synonymous OE1.12
01.21.6
LoF obs/exp: 10 / 13.6Missense obs/exp: 209 / 210.9Syn Z: -0.88
DN
0.6552th %ile
GOF
0.5170th %ile
LOF
0.3648th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

TRUB2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC