TRMT10C

Chr 3AR

tRNA methyltransferase 10C, mitochondrial RNase P subunit

Also known as: COXPD30, HNYA, MRPP1, RG9MTD1

The protein is a subunit of mitochondrial ribonuclease P that processes the 5' end of mitochondrial tRNAs and confers RNA-binding capacity essential for transcript processing, RNA modification, translation and mitochondrial respiration. Mutations cause combined oxidative phosphorylation deficiency 30 through an autosomal recessive inheritance pattern. The pathogenic mechanism involves loss of function, disrupting mitochondrial tRNA processing and subsequent oxidative phosphorylation.

OMIMResearchSummary from RefSeq, OMIM, UniProt, Mechanism
DNmechanismARLOEUF 1.141 OMIM phenotype
Clinical SummaryTRMT10C
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Gene-Disease Validity (ClinGen)
mitochondrial disease · ARModerate

Moderate evidence — consider for supplementary testing

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.14LOEUF
pLI 0.000
Z-score 1.22
OE 0.63 (0.371.14)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.77Z-score
OE missense 0.85 (0.750.96)
174 obs / 205.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.63 (0.371.14)
00.351.4
Missense OE0.85 (0.750.96)
00.61.4
Synonymous OE0.94
01.21.6
LoF obs/exp: 8 / 12.7Missense obs/exp: 174 / 205.0Syn Z: 0.39
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
strongTRMT10C-related mitochondrial RNA processing and multiple respiratory chain deficienciesOTHERAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6551th %ile
GOF
0.5269th %ile
LOF
0.2484th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

TRMT10C · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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