TPRN

Chr 9AR

taperin

Also known as: C9orf75, DFNB79

The TPRN protein is essential for hearing and required for maintenance of stereocilia on inner and outer hair cells, where it forms rings at the base of stereocilia and binds actin filaments to stabilize these structures. Mutations cause autosomal recessive deafness (DFNB79), affecting auditory function through disruption of hair cell stereocilia integrity. This gene follows autosomal recessive inheritance and is not highly constrained against loss-of-function variants.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 0.801 OMIM phenotype
Clinical SummaryTPRN
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Gene-Disease Validity (ClinGen)
nonsyndromic genetic hearing loss · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.01) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.80LOEUF
pLI 0.007
Z-score 2.13
OE 0.40 (0.220.80)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
-0.50Z-score
OE missense 1.08 (0.991.19)
307 obs / 283.5 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.40 (0.220.80)
00.351.4
Missense OE1.08 (0.991.19)
00.61.4
Synonymous OE1.21
01.21.6
LoF obs/exp: 6 / 14.9Missense obs/exp: 307 / 283.5Syn Z: -1.91
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveTPRN-related deafnessLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6164th %ile
GOF
0.6932th %ile
LOF
0.3940th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

TPRN · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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