TNFRSF12A

Chr 16

TNF receptor superfamily member 12A

Also known as: CD266, FN14, TWEAKR

The TNFRSF12A protein functions as a receptor for TNFSF12/TWEAK and regulates apoptosis, angiogenesis, endothelial cell proliferation, and wound healing. Mutations cause Opitz GBBB syndrome type 2, an X-linked disorder characterized by developmental abnormalities affecting multiple organ systems including craniofacial features, cardiac defects, and genitourinary anomalies. The gene shows tolerance to loss-of-function variants (pLI 0.018, LOEUF 1.53), suggesting haploinsufficiency may not be the primary disease mechanism.

OMIMResearchSummary from RefSeq, UniProt
GOFmechanismLOEUF 1.53
Clinical SummaryTNFRSF12A
Population Constraint (gnomAD)
Low constraint (pLI 0.02) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.53LOEUF
pLI 0.018
Z-score 0.78
OE 0.62 (0.281.53)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.14Z-score
OE missense 1.05 (0.851.30)
60 obs / 57.0 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.62 (0.281.53)
00.351.4
Missense OE1.05 (0.851.30)
00.61.4
Synonymous OE1.36
01.21.6
LoF obs/exp: 3 / 4.8Missense obs/exp: 60 / 57.0Syn Z: -1.40
DN
0.6065th %ile
GOF
0.7127th %ile
LOF
0.3357th %ile

The highest-scoring mechanism for this gene is gain-of-function.

GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

TNFRSF12A · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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