TMEM144

Chr 4

transmembrane protein 144

Also known as: SLC35G7

The TMEM144 protein is predicted to function as a carbohydrate transmembrane transporter, facilitating the transport of carbohydrates across cellular membranes. Mutations in TMEM144 cause autosomal recessive developmental and epileptic encephalopathy-106, typically presenting in infancy with seizures and developmental delays. This gene shows very low constraint against loss-of-function variants (pLI near zero), which is consistent with a recessive inheritance pattern where heterozygous carriers are typically unaffected.

Summary from RefSeq
Research Assistant →
0
Active trials
1
Pubs (1 yr)
33
P/LP submissions
0%
P/LP missense
1.35
LOEUF
Mechanism
Clinical SummaryTMEM144
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
33 unique Pathogenic / Likely Pathogenic· 58 VUS of 106 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.35LOEUF
pLI 0.000
Z-score 0.39
OE 0.90 (0.621.35)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.10Z-score
OE missense 1.02 (0.911.15)
184 obs / 180.2 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.90 (0.621.35)
00.351.4
Missense OE1.02 (0.911.15)
00.61.4
Synonymous OE1.20
01.21.6
LoF obs/exp: 17 / 18.8Missense obs/exp: 184 / 180.2Syn Z: -1.23

ClinVar Variant Classifications

106 submitted variants in ClinVar

Classification Summary

Pathogenic30
Likely Pathogenic3
VUS58
Likely Benign1
30
Pathogenic
3
Likely Pathogenic
58
VUS
1
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
30
0
30
Likely Pathogenic
0
0
3
0
3
VUS
0
51
7
0
58
Likely Benign
0
0
1
0
1
Benign
0
0
0
0
0
Total05141092

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

TMEM144 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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