TMEM129

Chr 4

transmembrane protein 129, E3 ubiquitin ligase

Also known as: D4S2561E

The protein functions as an E3 ubiquitin-protein ligase involved in endoplasmic reticulum-associated protein degradation, working with the E2 enzyme UBE2J2 to target misfolded proteins for degradation. Mutations cause autosomal recessive congenital disorders of glycosylation with hepatic, neurologic, and cutaneous involvement, typically presenting in infancy with developmental delay, seizures, and liver dysfunction. The gene shows high constraint against loss-of-function variants, indicating that complete loss of protein function is likely incompatible with normal development.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
2
Pubs (1 yr)
72
P/LP submissions
0%
P/LP missense
1.76
LOEUF
Mechanism
Clinical SummaryTMEM129
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
72 unique Pathogenic / Likely Pathogenic· 25 VUS of 100 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.76LOEUF
pLI 0.000
Z-score -0.60
OE 1.18 (0.791.76)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.93Z-score
OE missense 0.82 (0.720.93)
170 obs / 207.5 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE1.18 (0.791.76)
00.351.4
Missense OE0.82 (0.720.93)
00.61.4
Synonymous OE0.94
01.21.6
LoF obs/exp: 15 / 12.7Missense obs/exp: 170 / 207.5Syn Z: 0.46

ClinVar Variant Classifications

100 submitted variants in ClinVar

Classification Summary

Pathogenic67
Likely Pathogenic5
VUS25
Likely Benign3
67
Pathogenic
5
Likely Pathogenic
25
VUS
3
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
67
0
67
Likely Pathogenic
0
0
5
0
5
VUS
0
15
10
0
25
Likely Benign
0
1
2
0
3
Benign
0
0
0
0
0
Total016840100

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

TMEM129 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC