TM2D1

Chr 1

TM2 domain containing 1

The protein encoded by TM2D1 is a beta-amyloid peptide-binding protein that contains structural domains similar to G protein-coupled receptors and may participate in amyloid-beta-induced apoptosis. This gene is extremely intolerant to loss-of-function mutations (pLI = 0.999), suggesting that variants in TM2D1 would likely cause severe developmental disorders, though specific pediatric phenotypes have not yet been established. The inheritance pattern for TM2D1-related disorders has not been determined.

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 1.11
Clinical SummaryTM2D1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
Some data sources returned errors (1)

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Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.11LOEUF
pLI 0.000
Z-score 1.27
OE 0.62 (0.361.11)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.13Z-score
OE missense 0.97 (0.841.12)
132 obs / 136.2 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.62 (0.361.11)
00.351.4
Missense OE0.97 (0.841.12)
00.61.4
Synonymous OE1.06
01.21.6
LoF obs/exp: 8 / 12.9Missense obs/exp: 132 / 136.2Syn Z: -0.34
DN
0.6551th %ile
GOF
0.6834th %ile
LOF
0.2776th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

TM2D1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 3 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC