THYN1

Chr 11

thymocyte nuclear protein 1

Also known as: HSPC144, MDS012, MY105, THY28, THY28KD

The protein specifically binds 5-hydroxymethylcytosine (5hmC) and acts as a reader of this DNA modification, and may be involved in apoptosis induction. Mutations cause autosomal recessive neurodevelopmental disorder with seizures and brain atrophy. The gene shows extremely high constraint against loss-of-function variants, indicating it is essential for normal human development.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
0
Pubs (1 yr)
91
P/LP submissions
0%
P/LP missense
1.92
LOEUF
Mechanism
Clinical SummaryTHYN1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
90 unique Pathogenic / Likely Pathogenic· 50 VUS of 152 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.92LOEUF
pLI 0.000
Z-score -1.75
OE 1.52 (1.051.92)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.19Z-score
OE missense 0.95 (0.821.11)
120 obs / 125.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE1.52 (1.051.92)
00.351.4
Missense OE0.95 (0.821.11)
00.61.4
Synonymous OE1.22
01.21.6
LoF obs/exp: 20 / 13.1Missense obs/exp: 120 / 125.8Syn Z: -1.10

ClinVar Variant Classifications

152 submitted variants in ClinVar

Classification Summary

Pathogenic83
Likely Pathogenic7
VUS50
Likely Benign5
83
Pathogenic
7
Likely Pathogenic
50
VUS
5
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
83
0
83
Likely Pathogenic
0
0
7
0
7
VUS
0
38
12
0
50
Likely Benign
0
4
1
0
5
Benign
0
0
0
0
0
Total0421030145

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

THYN1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC