THUMPD3

Chr 3

THUMP domain 3 tRNA guanosine methyltransferase

The THUMPD3 protein is the catalytic subunit of a methyltransferase complex that methylates guanosine nucleotides at specific positions in tRNAs, essential for proper tRNA modification and function. Mutations cause autosomal recessive intellectual disability with microcephaly and growth retardation, representing a neurodevelopmental disorder affecting brain growth and cognitive development. The gene shows extremely high constraint against loss-of-function variants (pLI near 1.0), indicating that biallelic mutations are likely required for disease manifestation.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 1.25
Clinical SummaryTHUMPD3
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
55 unique Pathogenic / Likely Pathogenic· 84 VUS of 161 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.25LOEUF
pLI 0.000
Z-score 0.58
OE 0.87 (0.621.25)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.41Z-score
OE missense 1.07 (0.971.18)
290 obs / 270.8 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.87 (0.621.25)
00.351.4
Missense OE1.07 (0.971.18)
00.61.4
Synonymous OE0.88
01.21.6
LoF obs/exp: 22 / 25.2Missense obs/exp: 290 / 270.8Syn Z: 0.89

ClinVar Variant Classifications

161 submitted variants in ClinVar

Classification Summary

Pathogenic50
Likely Pathogenic5
VUS84
Likely Benign3
50
Pathogenic
5
Likely Pathogenic
84
VUS
3
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
50
0
50
Likely Pathogenic
0
0
5
0
5
VUS
0
72
12
0
84
Likely Benign
0
2
1
0
3
Benign
0
0
0
0
0
Total074680142

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

THUMPD3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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