THOC7

Chr 3

THO complex subunit 7

Also known as: NIF3L1BP1, fSAP24, hTREX30

The THOC7 protein is a component of the TREX complex that couples mRNA transcription, processing and nuclear export, and is required for efficient export of polyadenylated RNA from the nucleus to the cytoplasm. Mutations cause autosomal recessive intellectual developmental disorder with dysmorphic facies, seizures, and distal limb anomalies. This gene has moderate constraint against loss-of-function variants and is associated with a GeneReviews entry indicating established clinical significance.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 0.82
Clinical SummaryTHOC7
Population Constraint (gnomAD)
Low constraint (pLI 0.01) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.82LOEUF
pLI 0.006
Z-score 2.06
OE 0.42 (0.230.82)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
1.09Z-score
OE missense 0.70 (0.580.85)
76 obs / 107.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.42 (0.230.82)
00.351.4
Missense OE0.70 (0.580.85)
00.61.4
Synonymous OE1.13
01.21.6
LoF obs/exp: 6 / 14.4Missense obs/exp: 76 / 107.9Syn Z: -0.60
DN
0.75top 25%
GOF
0.6247th %ile
LOF
0.2680th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

THOC7 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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