TFDP1

Chr 13

transcription factor Dp-1

Also known as: DILC, DP1, DRTF1, Dp-1

The protein encoded by this gene heterodimerizes with E2F transcription factors to regulate genes involved in cell cycle progression from G1 to S phase and DNA replication. Mutations cause intellectual disability, microcephaly, and growth retardation with autosomal dominant inheritance. This gene is highly constrained against loss-of-function variants (pLI 0.97, LOEUF 0.32), indicating intolerance to protein-disrupting mutations.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
16
Pubs (1 yr)
117
P/LP submissions
0%
P/LP missense
0.32
LOEUF· LoF intol.
LOF
Mechanism· predicted
Clinical SummaryTFDP1
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 0.97). One damaged copy is likely sufficient to cause disease.
📋
ClinVar Variants
117 unique Pathogenic / Likely Pathogenic· 52 VUS of 198 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.32LOEUF
pLI 0.972
Z-score 3.71
OE 0.10 (0.040.32)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
2.28Z-score
OE missense 0.60 (0.530.69)
159 obs / 263.3 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.10 (0.040.32)
00.351.4
Missense OE0.60 (0.530.69)
00.61.4
Synonymous OE0.87
01.21.6
LoF obs/exp: 2 / 19.8Missense obs/exp: 159 / 263.3Syn Z: 1.08
DN
0.4190th %ile
GOF
0.2099th %ile
LOF
0.75top 10%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.32

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

198 submitted variants in ClinVar

Classification Summary

Pathogenic114
Likely Pathogenic3
VUS52
Likely Benign3
Benign2
114
Pathogenic
3
Likely Pathogenic
52
VUS
3
Likely Benign
2
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
114
0
114
Likely Pathogenic
0
0
3
0
3
VUS
0
37
15
0
52
Likely Benign
0
3
0
0
3
Benign
0
0
0
2
2
Total0401322174

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

TFDP1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →