The TEKT5 protein is a sperm-specific microtubule inner protein that forms part of the structural framework anchoring tektin bundles to the tubulin wall of sperm flagella, essential for proper sperm motility. Mutations cause male infertility due to defective sperm function, following an autosomal recessive inheritance pattern. This gene shows low constraint against loss-of-function variants, consistent with its specialized reproductive function that does not affect survival.

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 1.67
Clinical SummaryTEKT5
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.67LOEUF
pLI 0.000
Z-score -0.96
OE 1.22 (0.901.67)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-1.95Z-score
OE missense 1.31 (1.211.42)
409 obs / 312.1 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.22 (0.901.67)
00.351.4
Missense OE1.31 (1.211.42)
00.61.4
Synonymous OE1.25
01.21.6
LoF obs/exp: 27 / 22.1Missense obs/exp: 409 / 312.1Syn Z: -2.29
DN
0.75top 25%
GOF
0.7127th %ile
LOF
0.2871th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

TEKT5 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →