TECPR2

Chr 14AR

tectonin beta-propeller repeat containing 2

Also known as: HSAN9, KIAA0329, SPG49

The TECPR2 protein functions as a positive regulator of autophagy, the cellular process that degrades damaged organelles and proteins. Autosomal recessive mutations cause hereditary sensory and autonomic neuropathy type IX with developmental delay, affecting both the peripheral nervous system and early neurodevelopment. The gene is highly constrained against loss-of-function variation (LOEUF 0.346), indicating that complete loss of protein function is likely not well tolerated.

GeneReviewsOMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 0.351 OMIM phenotype
Clinical SummaryTECPR2
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.58) — some intolerance to loss-of-function variants.
📋
ClinVar Variants
48 unique Pathogenic / Likely Pathogenic· 137 VUS of 400 total submissions
📖
GeneReview available — TECPR2
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.35LOEUF
pLI 0.580
Z-score 5.60
OE 0.22 (0.140.35)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
1.74Z-score
OE missense 0.83 (0.780.88)
689 obs / 829.9 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.22 (0.140.35)
00.351.4
Missense OE0.83 (0.780.88)
00.61.4
Synonymous OE1.00
01.21.6
LoF obs/exp: 13 / 59.7Missense obs/exp: 689 / 829.9Syn Z: 0.02

ClinVar Variant Classifications

400 submitted variants in ClinVar

Classification Summary

Pathogenic26
Likely Pathogenic22
VUS137
Likely Benign213
Benign1
Conflicting1
26
Pathogenic
22
Likely Pathogenic
137
VUS
213
Likely Benign
1
Benign
1
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
19
1
5
1
26
Likely Pathogenic
21
0
1
0
22
VUS
0
122
10
5
137
Likely Benign
0
4
84
125
213
Benign
0
0
1
0
1
Conflicting
1
Total40127101131400

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

TECPR2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →