TBL3

Chr 16

transducin beta like 3

Also known as: SAZD, UTP13

TBL3 encodes a WD40 repeat-containing protein that is part of the small subunit processome involved in ribosome biogenesis, where it assists in the processing and assembly of precursor ribosomal RNA in the nucleolus. Mutations cause an autosomal recessive neurodevelopmental disorder characterized by intellectual disability, developmental delay, and microcephaly. This gene is not highly constrained against loss-of-function variation, which is consistent with the recessive inheritance pattern observed in affected individuals.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 0.74
Clinical SummaryTBL3
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
42 unique Pathogenic / Likely Pathogenic· 284 VUS of 392 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.74LOEUF
pLI 0.000
Z-score 2.97
OE 0.53 (0.380.74)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
-0.21Z-score
OE missense 1.03 (0.951.10)
540 obs / 526.7 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.53 (0.380.74)
00.351.4
Missense OE1.03 (0.951.10)
00.61.4
Synonymous OE1.20
01.21.6
LoF obs/exp: 24 / 45.6Missense obs/exp: 540 / 526.7Syn Z: -2.42

ClinVar Variant Classifications

392 submitted variants in ClinVar

Classification Summary

Pathogenic41
Likely Pathogenic1
VUS284
Likely Benign23
Benign3
41
Pathogenic
1
Likely Pathogenic
284
VUS
23
Likely Benign
3
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
41
0
41
Likely Pathogenic
0
0
1
0
1
VUS
1
267
16
0
284
Likely Benign
1
18
0
4
23
Benign
0
0
1
2
3
Total2285596352

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

TBL3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC