TAX1BP3

Chr 17

Tax1 binding protein 3

Also known as: TIP-1, TIP1

The protein contains a PDZ domain that mediates protein-protein interactions, regulating cell signaling pathways including Wnt/beta-catenin signaling and modulating potassium channel localization. Mutations cause autosomal recessive developmental and epileptic encephalopathy with onset in infancy, characterized by severe intellectual disability, refractory seizures, and progressive microcephaly. The gene shows tolerance to loss-of-function variants in the general population.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 1.49
Clinical SummaryTAX1BP3
Population Constraint (gnomAD)
Low constraint (pLI 0.01) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
34 unique Pathogenic / Likely Pathogenic· 57 VUS of 110 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.49LOEUF
pLI 0.005
Z-score 0.76
OE 0.66 (0.331.49)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.90Z-score
OE missense 0.72 (0.590.90)
60 obs / 83.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.66 (0.331.49)
00.351.4
Missense OE0.72 (0.590.90)
00.61.4
Synonymous OE0.83
01.21.6
LoF obs/exp: 4 / 6.0Missense obs/exp: 60 / 83.0Syn Z: 0.78

ClinVar Variant Classifications

110 submitted variants in ClinVar

Classification Summary

Pathogenic32
Likely Pathogenic2
VUS57
Likely Benign6
Benign9
Conflicting2
32
Pathogenic
2
Likely Pathogenic
57
VUS
6
Likely Benign
9
Benign
2
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
32
0
32
Likely Pathogenic
0
0
2
0
2
VUS
1
27
29
0
57
Likely Benign
0
0
5
1
6
Benign
0
1
5
3
9
Conflicting
2
Total128734108

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

TAX1BP3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC