SYTL4

Chr X

synaptotagmin like 4

Also known as: SLP4

The protein modulates exocytosis of dense-core granules and secretion of hormones in the pancreas and pituitary through its interaction with Rab27 and membrane trafficking pathways. Mutations cause autosomal recessive arthrogryposis, a congenital condition characterized by joint contractures present at birth. The gene is not highly constrained against loss-of-function variants, consistent with recessive inheritance requiring biallelic mutations to cause disease.

Summary from RefSeq, UniProt
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0
Active trials
4
Pubs (1 yr)
0
P/LP submissions
P/LP missense
0.57
LOEUF
Multiple*
Mechanism· predicted
Clinical SummarySYTL4
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.31) despite low pLI — interpret in context.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.57LOEUF
pLI 0.014
Z-score 3.21
OE 0.31 (0.180.57)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
0.81Z-score
OE missense 0.86 (0.770.96)
222 obs / 258.7 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.31 (0.180.57)
00.351.4
Missense OE0.86 (0.770.96)
00.61.4
Synonymous OE0.71
01.21.6
LoF obs/exp: 8 / 25.5Missense obs/exp: 222 / 258.7Syn Z: 2.15
DN
0.75top 25%
GOF
0.7027th %ile
LOF
0.3844th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SYTL4 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC