SYNPR

Chr 3

synaptoporin

Also known as: SPO

The SYNPR protein is an intrinsic membrane protein of small synaptic vesicles that functions as a probable vesicular channel protein involved in modulating chemical synaptic transmission. Mutations in SYNPR have not been definitively associated with human disease based on the available data. The gene shows tolerance to loss-of-function variants (pLI 0.004, LOEUF 0.88), suggesting that complete loss of function may not be highly pathogenic.

ResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 0.88
Clinical SummarySYNPR
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.88LOEUF
pLI 0.004
Z-score 1.89
OE 0.45 (0.240.88)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.42Z-score
OE missense 0.91 (0.791.04)
141 obs / 155.7 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.45 (0.240.88)
00.351.4
Missense OE0.91 (0.791.04)
00.61.4
Synonymous OE1.13
01.21.6
LoF obs/exp: 6 / 13.5Missense obs/exp: 141 / 155.7Syn Z: -0.79
DN
0.77top 25%
GOF
0.75top 25%
LOF
0.2581th %ile

This gene has evidence for multiple mechanisms of pathogenicity (dominant-negative and gain-of-function). Both the Badonyi & Marsh prediction and the broader genomic evidence point to dominant-negative as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

DNprediction above median
GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SYNPR · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC