SUN5

Chr 20AR

Sad1 and UNC84 domain containing 5

Also known as: SPAG4L, SPGF16, TSARG4, dJ726C3.1

SUN5 encodes a protein that anchors the sperm head to the tail by attaching the coupling apparatus to the sperm nuclear envelope during spermatogenesis. Mutations cause autosomal recessive spermatogenic failure, specifically acephalic spermatozoa syndrome where sperm heads detach from tails. This gene is not highly constrained in the general population and primarily affects male fertility rather than causing neurological disease.

Summary from RefSeq, OMIM, UniProt
Research Assistant →

Primary Disease Associations & Inheritance

Spermatogenic failure 16MIM #617187
AR
0
Active trials
7
Pubs (1 yr)
31
P/LP submissions
15%
P/LP missense
1.25
LOEUF
Mechanism
Clinical SummarySUN5
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
26 unique Pathogenic / Likely Pathogenic· 57 VUS of 90 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.25LOEUF
pLI 0.000
Z-score 0.57
OE 0.88 (0.631.25)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.69Z-score
OE missense 0.87 (0.770.98)
186 obs / 214.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.88 (0.631.25)
00.351.4
Missense OE0.87 (0.770.98)
00.61.4
Synonymous OE0.90
01.21.6
LoF obs/exp: 22 / 25.1Missense obs/exp: 186 / 214.4Syn Z: 0.72

ClinVar Variant Classifications

90 submitted variants in ClinVar

Classification Summary

Pathogenic19
Likely Pathogenic7
VUS57
Likely Benign3
Benign1
19
Pathogenic
7
Likely Pathogenic
57
VUS
3
Likely Benign
1
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
3
16
0
19
Likely Pathogenic
1
1
5
0
7
VUS
0
53
3
1
57
Likely Benign
0
1
1
1
3
Benign
0
0
1
0
1
Total15826287

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

SUN5 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗