STRAP

Chr 12

serine/threonine kinase receptor associated protein

Also known as: MAWD, PT-WD, UNRIP

The STRAP protein is a component of the SMN complex that catalyzes the assembly of small nuclear ribonucleoproteins (snRNPs), which are essential building blocks of the spliceosome responsible for pre-mRNA splicing. This gene is highly constrained against loss-of-function variants (pLI=0.90, LOEUF=0.375), suggesting that mutations would likely cause severe developmental consequences, though no specific Mendelian disease has been definitively associated with STRAP mutations to date. Given its critical role in RNA splicing machinery and high constraint scores, pathogenic variants would be expected to follow an autosomal dominant inheritance pattern.

Summary from RefSeq, UniProt
Research Assistant →
6
Active trials
155
Pubs (1 yr)
37
P/LP submissions
0%
P/LP missense
0.38
LOEUF
LOF
Mechanism· predicted
Clinical SummarySTRAP
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 0.90). One damaged copy is likely sufficient to cause disease.
📋
ClinVar Variants
37 unique Pathogenic / Likely Pathogenic· 32 VUS of 92 total submissions
💊
Clinical Trials
6 active or recruiting trials — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.38LOEUF
pLI 0.901
Z-score 3.60
OE 0.14 (0.070.38)
Highly constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
2.08Z-score
OE missense 0.57 (0.490.67)
106 obs / 185.5 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.14 (0.070.38)
00.351.4
Missense OE0.57 (0.490.67)
00.61.4
Synonymous OE0.83
01.21.6
LoF obs/exp: 3 / 20.7Missense obs/exp: 106 / 185.5Syn Z: 1.05
DN
0.3594th %ile
GOF
0.4085th %ile
LOF
0.68top 10%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.38

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

92 submitted variants in ClinVar

Classification Summary

Pathogenic35
Likely Pathogenic2
VUS32
Likely Benign1
35
Pathogenic
2
Likely Pathogenic
32
VUS
1
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
35
0
35
Likely Pathogenic
0
0
2
0
2
VUS
0
23
9
0
32
Likely Benign
0
0
1
0
1
Benign
0
0
0
0
0
Total02347070

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

STRAP · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

Vagus Nerve Autonomic DisorderHeart RatePain

Balance, Autonomic Response, and Sensory Modulation to Dosage of Mechanical Vagal Stimulation in Healthy Adults

RECRUITING
NCT06541808Phase NAUniversity of ViennaStarted 2024-12-02
mechanical Vagus Nerve Stimulation (Low Intensity)mechanical Vagus Nerve Stimulation (Intermediate Intensity)mechanical Vagus Nerve Stimulation (High Intensity)
Muscular DystrophyFacioscapulohumeral

Clinical Trial Readiness Network FSHD France: Prospective 24 Months MRI Study

ACTIVE NOT RECRUITING
NCT04038138Phase NACentre Hospitalier Universitaire de NiceStarted 2019-09-16
Validation of new COA for FSHD patients
Neuromuscular Diseases

The Neuroimage Study of the Neuromuscular Disorders.

RECRUITING
NCT05048862National Taiwan University HospitalStarted 2021-08-01
Neuromuscular ultrasoundMuscle MRINerve conduction studies and autonomic function tests
AgingCardiovascular Risk Factor

A Combined Multidomain Intervention to Prevent Cognitive Decline Associated With Cardiovascular Risk Factors.

RECRUITING
NCT04962061Phase NALouis BhererStarted 2021-09-01
Cognitive TrainingAerobic and resistance exercisesStretching and Toning
Muscular Dystrophy, Facioscapulohumeral

Clenbuterol to Target DUX4 in FSHD

RECRUITING
NCT06721299Phase PHASE1Jeffrey StatlandStarted 2025-06-25
Clenbuterol
ObesityMetabolic DiseaseCold Exposure

Thermogenic Silencer Regulatory Factors in Humans

RECRUITING
NCT06424132Phase NARockefeller UniversityStarted 2024-08-16
Cold Vest Exposure PeriodRewarming Exposure PeriodFasting
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗