STAU1

Chr 20

staufen double-stranded RNA binding protein 1

Also known as: PPP1R150, STAU

The protein binds double-stranded RNA and tubulin to transport and localize mRNAs to specific cellular sites via the microtubule network, particularly to the rough endoplasmic reticulum for translation. Mutations cause autosomal dominant neurological disorders affecting the central nervous system. This gene is extremely intolerant to loss-of-function mutations, indicating that even single functional copies are insufficient for normal development.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
15
Pubs (1 yr)
8
P/LP submissions
0%
P/LP missense
0.17
LOEUF· LoF intol.
LOF
Mechanism· predicted
Clinical SummarySTAU1
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.
📋
ClinVar Variants
8 unique Pathogenic / Likely Pathogenic· 64 VUS of 87 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.17LOEUF
pLI 1.000
Z-score 4.76
OE 0.04 (0.010.17)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
1.93Z-score
OE missense 0.70 (0.630.78)
225 obs / 322.6 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.04 (0.010.17)
00.351.4
Missense OE0.70 (0.630.78)
00.61.4
Synonymous OE1.11
01.21.6
LoF obs/exp: 1 / 28.3Missense obs/exp: 225 / 322.6Syn Z: -0.97
DN
0.3992th %ile
GOF
0.3788th %ile
LOF
0.80top 5%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.17

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

87 submitted variants in ClinVar

Classification Summary

Pathogenic6
Likely Pathogenic2
VUS64
Likely Benign2
Benign1
6
Pathogenic
2
Likely Pathogenic
64
VUS
2
Likely Benign
1
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
6
0
6
Likely Pathogenic
0
0
2
0
2
VUS
0
56
8
0
64
Likely Benign
0
1
1
0
2
Benign
0
0
1
0
1
Total05718075

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

STAU1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗