ST8SIA6

Chr 10

ST8 alpha-N-acetyl-neuraminide alpha-2,8-sialyltransferase 6

Also known as: SIA8F, SIAT8-F, SIAT8F, ST8SIA-VI, ST8SiaVI

This gene encodes an alpha-2,8-sialyltransferase that adds sialic acid residues to O-glycans, with the minimal acceptor substrate being NeuAc-alpha-2,3(6)-Gal sequences. Pathogenic variants cause autosomal recessive intellectual developmental disorder with seizures, hypotonia, and brain abnormalities. The gene is not highly constrained against loss-of-function variants, consistent with the recessive inheritance pattern observed in affected individuals.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
7
Pubs (1 yr)
13
P/LP submissions
0%
P/LP missense
1.57
LOEUF
Mechanism
Clinical SummaryST8SIA6
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
13 unique Pathogenic / Likely Pathogenic· 54 VUS of 81 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.57LOEUF
pLI 0.000
Z-score -0.03
OE 1.01 (0.671.57)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.43Z-score
OE missense 1.09 (0.971.23)
199 obs / 182.6 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.01 (0.671.57)
00.351.4
Missense OE1.09 (0.971.23)
00.61.4
Synonymous OE1.17
01.21.6
LoF obs/exp: 14 / 13.9Missense obs/exp: 199 / 182.6Syn Z: -1.15

ClinVar Variant Classifications

81 submitted variants in ClinVar

Classification Summary

Pathogenic13
VUS54
Likely Benign1
Benign1
13
Pathogenic
54
VUS
1
Likely Benign
1
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
13
0
13
Likely Pathogenic
0
0
0
0
0
VUS
0
46
8
0
54
Likely Benign
0
1
0
0
1
Benign
0
0
1
0
1
Total04722069

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ST8SIA6 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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