SRD5A3

Chr 4AR

steroid 5 alpha-reductase 3

Also known as: CDG1P, CDG1Q, KRIZI, S5AR, S5AR 3, SRD5A2L, SRD5A2L1

The protein functions as a polyprenol reductase that converts polyprenol to dolichol in the early steps of protein N-linked glycosylation and also converts testosterone to dihydrotestosterone. Biallelic mutations cause congenital disorder of glycosylation type Iq and Kahrizi syndrome, both presenting with intellectual disability and developmental delays along with multisystem involvement including cerebellar ataxia and ophthalmologic abnormalities. This follows autosomal recessive inheritance.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 0.972 OMIM phenotypes
Clinical SummarySRD5A3
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Gene-Disease Validity (ClinGen)
SRD5A3-congenital disorder of glycosylation · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.97LOEUF
pLI 0.000
Z-score 1.64
OE 0.54 (0.320.97)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.76Z-score
OE missense 0.83 (0.720.96)
136 obs / 163.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.54 (0.320.97)
00.351.4
Missense OE0.83 (0.720.96)
00.61.4
Synonymous OE0.88
01.21.6
LoF obs/exp: 8 / 14.8Missense obs/exp: 136 / 163.3Syn Z: 0.80
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveSRD5A3-related congenital disorder of glycosylationLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.7228th %ile
GOF
0.6542th %ile
LOF
0.2190th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SRD5A3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗