SPATA8

Chr 15

spermatogenesis associated 8

Also known as: SRG8

The protein localizes to the sperm flagellum and is required for normal sperm motility and male fertility. Mutations cause autosomal recessive primary ciliary dyskinesia, a disorder affecting respiratory cilia function that typically presents in infancy or early childhood with chronic respiratory infections, bronchiectasis, and often situs inversus. The gene shows moderate tolerance to loss-of-function variants, consistent with its role in a recessive ciliopathy.

DNmechanismLOEUF 1.49
Clinical SummarySPATA8
Population Constraint (gnomAD)
Low constraint (pLI 0.07) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.49LOEUF
pLI 0.070
Z-score 0.94
OE 0.50 (0.201.49)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.35Z-score
OE missense 1.13 (0.931.38)
67 obs / 59.4 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.50 (0.201.49)
00.351.4
Missense OE1.13 (0.931.38)
00.61.4
Synonymous OE1.13
01.21.6
LoF obs/exp: 2 / 4.0Missense obs/exp: 67 / 59.4Syn Z: -0.52
DN
0.80top 10%
GOF
0.6151th %ile
LOF
0.3648th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SPATA8 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found