SOX11

Chr 2AD

SRY-box transcription factor 11

Also known as: CSS9, IDDMOH, MRD27

SOX11 encodes a transcription factor that binds to gene promoters to activate transcription and plays a critical role in cell survival during development of the neural tube, branchial arches, and somites. Mutations cause autosomal dominant intellectual developmental disorder with microcephaly and variable features including ocular malformations or hypogonadotropic hypogonadism. The gene is highly constrained against loss-of-function variants, reflecting its essential role in neurodevelopment.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismADLOEUF 0.441 OMIM phenotype
Clinical SummarySOX11
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Gene-Disease Validity (ClinGen)
SOX11-related complex neurodevelopmental disorder with or without congenital anomalies · ADDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.86) — some intolerance to loss-of-function variants.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.44LOEUF
pLI 0.858
Z-score 2.76
OE 0.09 (0.030.44)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
2.26Z-score
OE missense 0.59 (0.520.68)
146 obs / 245.6 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.09 (0.030.44)
00.351.4
Missense OE0.59 (0.520.68)
00.61.4
Synonymous OE1.35
01.21.6
LoF obs/exp: 1 / 10.8Missense obs/exp: 146 / 245.6Syn Z: -2.95
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveSOX11-related neurodevelopmental disorderOTHERAD
DN
0.2997th %ile
GOF
0.3193th %ile
LOF
0.83top 5%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · 1 literature citation · LOEUF 0.44

Literature Evidence

LOFDeletion 2p25.2: a cryptic chromosome abnormality in a patient with autism and mental retardation detected using aCGHPMID:18992374

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SOX11 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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