SLC6A19

Chr 5AR

solute carrier family 6 member 19

Also known as: B0AT1, HND

The protein functions as a sodium-dependent transporter that mediates resorption of neutral amino acids across the apical membrane of renal and intestinal epithelial cells, requiring accessory proteins (CLTRN in kidney, ACE2 in intestine) for proper cell surface expression and activity. Mutations cause Hartnup disorder, an autosomal recessive condition characterized by pellagra-like symptoms, cerebellar ataxia, and psychosis. The gene shows very low constraint against loss-of-function variants (LOEUF 1.42), consistent with the recessive inheritance pattern where heterozygous carriers are typically unaffected.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 1.421 OMIM phenotype
Clinical SummarySLC6A19
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Gene-Disease Validity (ClinGen)
Hartnup disease · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.42LOEUF
pLI 0.000
Z-score -0.38
OE 1.07 (0.821.42)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.04Z-score
OE missense 1.01 (0.931.09)
388 obs / 385.8 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.07 (0.821.42)
00.351.4
Missense OE1.01 (0.931.09)
00.61.4
Synonymous OE1.16
01.21.6
LoF obs/exp: 35 / 32.6Missense obs/exp: 388 / 385.8Syn Z: -1.67
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveSLC6A19-related Hartnup diseaseLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.74top 25%
GOF
0.84top 5%
LOF
0.2190th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SLC6A19 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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