SLC3A1

Chr 2ADAR

solute carrier family 3 member 1

Also known as: ATR1, CSNU1, D2H, NBAT, RBAT

This protein serves as a chaperone that facilitates the formation and trafficking of amino acid transporter complexes, particularly mediating renal reabsorption of cystine and dibasic amino acids in the proximal tubules. Mutations cause cystinuria, a disorder of amino acid transport that leads to kidney stone formation due to impaired cystine reabsorption. The condition shows both autosomal dominant and autosomal recessive inheritance patterns depending on the specific mutation.

GeneReviewsOMIMResearchSummary from RefSeq, OMIM, UniProt
AD/ARLOEUF 1.621 OMIM phenotype
Clinical SummarySLC3A1
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Gene-Disease Validity (ClinGen)
cystinuria · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
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ClinVar Variants
99 unique Pathogenic / Likely Pathogenic· 220 VUS of 400 total submissions
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GeneReview available — SLC3A1
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.62LOEUF
pLI 0.000
Z-score -1.16
OE 1.23 (0.941.62)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-3.14Z-score
OE missense 1.45 (1.351.56)
559 obs / 385.4 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.23 (0.941.62)
00.351.4
Missense OE1.45 (1.351.56)
00.61.4
Synonymous OE1.25
01.21.6
LoF obs/exp: 36 / 29.3Missense obs/exp: 559 / 385.4Syn Z: -2.34

ClinVar Variant Classifications

400 submitted variants in ClinVar

Classification Summary

Pathogenic57
Likely Pathogenic42
VUS220
Likely Benign48
Benign4
Conflicting19
57
Pathogenic
42
Likely Pathogenic
220
VUS
48
Likely Benign
4
Benign
19
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
24
4
29
0
57
Likely Pathogenic
18
22
2
0
42
VUS
3
190
21
6
220
Likely Benign
0
3
19
26
48
Benign
0
0
2
2
4
Conflicting
19
Total452197334390

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

SLC3A1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
Open Research Assistant →