SLC35D4

Chr 18

solute carrier family 35 member D4

Also known as: C18orf45, TMEM241, hVVT

The protein functions as a Golgi-localized UDP-N-acetylglucosamine transporter that transports UDP-GlcNAc into the Golgi lumen and contributes to lysosomal targeting of NPC2 through the mannose-6-phosphate modification pathway. Mutations cause autosomal recessive developmental and epileptic encephalopathy with early infantile onset. The condition involves severe neurological impairment with seizures beginning in infancy.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
0
Pubs (1 yr)
33
P/LP submissions
0%
P/LP missense
LOEUF
Mechanism
Clinical SummarySLC35D4
📋
ClinVar Variants
31 unique Pathogenic / Likely Pathogenic· 10 VUS of 59 total submissions
Some data sources returned errors (2)

ensembl: Error: Ensembl fetch failed: 400 for https://rest.ensembl.org/lookup/symbol/homo_sapiens/SLC35D4?content-type=application/json&expand=1

gnomad: Error: Gene not found

Population Genetics & Constraint

Constraint data not available from gnomAD.

ClinVar Variant Classifications

59 submitted variants in ClinVar

Classification Summary

Pathogenic30
Likely Pathogenic1
VUS10
30
Pathogenic
1
Likely Pathogenic
10
VUS

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
30
0
30
Likely Pathogenic
0
0
1
0
1
VUS
0
8
2
0
10
Likely Benign
0
0
0
0
0
Benign
0
0
0
0
0
Total0833041

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

SLC35D4 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 1 full-text resultsSearch PubTator3 ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found