SGSH

Chr 17AR

N-sulfoglucosamine sulfohydrolase

Also known as: HSS, MPS3A, SFMD

This gene encodes the enzyme sulfamidase; one of several enzymes involved in the lysosomal degradation of heparan sulfate. Mutations in this gene are associated with the lysosomal storage disease mucopolysaccaridosis IIIA, also known as Sanfilippo syndrome A, which results from impaired degradation of heparan sulfate. Transcripts of varying sizes have been reported but their biological validity has not been determined. [provided by RefSeq, Jun 2017]

GeneReviewsOMIMResearchGenerating clinical summary…

Primary Disease Associations & Inheritance

Mucopolysaccharidosis type IIIA (Sanfilippo A)MIM #252900
AR

Clinical highlights

Gene-disease validity (ClinGen)
mucopolysaccharidosis type 3A · ARDefinitivesufficient evidence for diagnostic panels
Interpreting a novel variant
Loss of function is the curated mechanism (Gene2Phenotype), though the gene is not strongly LoF-constrained in the population — weigh truncating variants against that tolerance.Curated gene-level mechanism — a prior for triage, not a per-variant call.
3
Active trials
21
Pubs (1 yr)
P/LP submissions
P/LP missense
0.80
LOEUF
LOF
Mechanism· G2P
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GeneReview available — SGSH
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Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint?
0.80LOEUF
pLI 0.000
Z-score 2.24
OE 0.47 (0.290.80)
Tolerant

Typical tolerance to LoF variation

Missense Constraint?
-0.05Z-score
OE missense 1.01 (0.921.10)
336 obs / 333.2 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios?
LoF OE?0.47 (0.290.80)
00.351.4
Missense OE?1.01 (0.921.10)
00.61.4
Synonymous OE?1.09
01.21.6
LoF obs/exp: 10 / 21.1Missense obs/exp: 336 / 333.2Syn Z: -0.91

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SGSH · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.