SFTPB

Chr 2AR

surfactant protein B

Also known as: PSP-B, SFTB3, SFTP3, SMDP1, SP-B

Surfactant protein B is an amphipathic protein that reduces surface tension at the air-liquid interface in alveoli and enhances the spreading and stability of pulmonary surfactant monolayers essential for lung function after birth. Mutations cause surfactant metabolism dysfunction type 1 (pulmonary alveolar proteinosis due to surfactant protein B deficiency), which presents with fatal respiratory distress in the neonatal period. This condition follows autosomal recessive inheritance.

OMIMResearchSummary from RefSeq, OMIM, UniProt
MultiplemechanismARLOEUF 0.721 OMIM phenotype
Clinical SummarySFTPB
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Gene-Disease Validity (ClinGen)
surfactant metabolism dysfunction, pulmonary, 1 · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.72LOEUF
pLI 0.000
Z-score 2.59
OE 0.42 (0.260.72)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.60Z-score
OE missense 0.89 (0.791.00)
202 obs / 227.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.42 (0.260.72)
00.351.4
Missense OE0.89 (0.791.00)
00.61.4
Synonymous OE0.94
01.21.6
LoF obs/exp: 10 / 23.6Missense obs/exp: 202 / 227.3Syn Z: 0.49
DN
0.75top 25%
GOF
0.77top 25%
LOF
0.1993th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SFTPB · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗