SENP3

Chr 17

SUMO specific peptidase 3

Also known as: SMT3IP1, SSP3, Ulp1

SENP3 encodes a SUMO-specific protease that removes SUMO2 and SUMO3 modifications from target proteins, regulating processes including ribosomal RNA processing, transcriptional activation, and DNA repair. The gene is highly constrained against loss-of-function variants (pLI = 0.85, LOEUF = 0.36), but specific disease associations and inheritance patterns have not yet been established in the provided data.

OMIMResearchSummary from RefSeq, UniProt
LOFmechanismLOEUF 0.36
Clinical SummarySENP3
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.85) — some intolerance to loss-of-function variants.
📋
ClinVar Variants
21 unique Pathogenic / Likely Pathogenic· 62 VUS of 84 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.36LOEUF
pLI 0.848
Z-score 4.32
OE 0.18 (0.100.36)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
2.56Z-score
OE missense 0.61 (0.540.68)
204 obs / 336.2 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.18 (0.100.36)
00.351.4
Missense OE0.61 (0.540.68)
00.61.4
Synonymous OE0.97
01.21.6
LoF obs/exp: 6 / 32.6Missense obs/exp: 204 / 336.2Syn Z: 0.30
DN
0.3296th %ile
GOF
0.4480th %ile
LOF
0.68top 25%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.36

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

84 submitted variants in ClinVar

Classification Summary

Pathogenic20
Likely Pathogenic1
VUS62
Likely Benign1
20
Pathogenic
1
Likely Pathogenic
62
VUS
1
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
20
0
20
Likely Pathogenic
0
0
1
0
1
VUS
0
53
9
0
62
Likely Benign
0
0
0
1
1
Benign
0
0
0
0
0
Total05330184

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

SENP3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →