SELENOS

Chr 15

selenoprotein S

The protein is a transmembrane selenoprotein in the endoplasmic reticulum that facilitates degradation of misfolded proteins by linking retrotranslocation machinery to the proteasome system. Mutations cause SELENOS-related myopathy, an autosomal recessive disorder characterized by early-onset progressive muscle weakness and rigidity affecting axial muscles, with some patients developing cataracts and hearing loss. The gene shows very low constraint against loss-of-function variants, consistent with its recessive inheritance pattern.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 1.69
Clinical SummarySELENOS
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
Some data sources returned errors (1)

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Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.69LOEUF
pLI 0.000
Z-score -0.28
OE 1.09 (0.701.69)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.61Z-score
OE missense 1.18 (1.011.38)
112 obs / 95.2 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.09 (0.701.69)
00.351.4
Missense OE1.18 (1.011.38)
00.61.4
Synonymous OE1.06
01.21.6
LoF obs/exp: 13 / 12.0Missense obs/exp: 112 / 95.2Syn Z: -0.30
DN
0.6938th %ile
GOF
0.5269th %ile
LOF
0.3261th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SELENOS · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗