SCN1A

Chr 2AD

sodium voltage-gated channel alpha subunit 1

Also known as: DEE6, DEE6A, DEE6B, DRVT, EIEE6, FEB3, FEB3A, FHM3

This gene encodes a voltage-gated sodium channel alpha subunit that controls sodium influx and is essential for action potential generation and propagation in neurons. Mutations cause a spectrum of epileptic disorders including Dravet syndrome, developmental and epileptic encephalopathy, generalized epilepsy with febrile seizures plus, familial febrile seizures, and familial hemiplegic migraine through autosomal dominant inheritance. Disease mechanisms are variant-dependent, with truncating mutations typically causing haploinsufficiency while specific missense variants can produce gain-of-function or dominant-negative effects.

GeneReviewsOMIMResearchSummary from RefSeq, OMIM, UniProt, Mechanism
GOF/LOFmechanismADLOEUF 0.075 OMIM phenotypes
VCEP Guidelines: Epilepsy Sodium ChannelReleased
View SpecificationsClinGen Panel
Clinical SummarySCN1A
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Gene-Disease Validity (ClinGen)
generalized epilepsy with febrile seizures plus · ADDefinitive

Definitive — sufficient evidence for diagnostic panels

4 total gene-disease associations curated

Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.
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Clinical Trials
8 active or recruiting trials — potential therapeutic options may be available
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GeneReview available — SCN1A
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Dual constrained — LoF & missense intolerant
LoF Constraint
0.07LOEUF
pLI 1.000
Z-score 8.52
OE 0.02 (0.010.07)
Highly constrained

Among the most LoF-intolerant genes (~top 3%)

Missense Constraint
5.22Z-score
OE missense 0.55 (0.510.59)
590 obs / 1070.7 exp
Constrained

Extremely missense-constrained (top ~0.01%)

Observed / Expected Ratios
LoF OE0.02 (0.010.07)
00.351.4
Missense OE0.55 (0.510.59)
00.61.4
Synonymous OE0.94
01.21.6
LoF obs/exp: 2 / 88.5Missense obs/exp: 590 / 1070.7Syn Z: 0.88
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveSCN1A-related seizure disordersLOFAD
Mechanism Note (variant-dependent)
GOFLOF— mechanism depends on specific variant

Nav1.1 is the most commonly mutated gene in epilepsy. LOF (truncation, severe missense with loss of current) causes Dravet syndrome via reduced inhibitory interneuron firing. GOF missense variants (increased persistent current) cause GEFS+. Mechanism is variant- and phenotype-dependent.

DN
0.5477th %ile
GOF
0.79top 25%
LOF
0.53top 25%

This gene has evidence for multiple mechanisms of pathogenicity (loss-of-function and gain-of-function). The Badonyi & Marsh model scores gain-of-function highest among its predictions, but genomic evidence (constraint, ClinVar variant spectrum, and literature) most strongly supports loss-of-function (haploinsufficiency). Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

LOF1 literature citation · LOEUF 0.07
GOFprediction above median · 1 literature citation

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Literature Evidence

GOFSCN1A mutations alter channel inactivation, resulting in persistent inward sodium current. This gain-of-function abnormality will likely enhance excitability of neuronal membranes by causing prolonged membrane depolarization, a plausible underlying biophysical mechanism responsible for this inheritePMID:12086636
LOFHer early myoclonic seizures were likely due to haploinsufficiency of SCN1A and SCN2A, which are included in the deletion region.PMID:20358620

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SCN1A · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

Dravet Syndrome

Longitudinal Study of Phenotypic and Developmental Severity in Patients With Dravet Syndrome With SCN1A Gene Mutation

RECRUITING
NCT07251673Assistance Publique - Hôpitaux de ParisStarted 2025-09-15
16P11.2 Deletion Syndrome16p11.2 Duplications1Q21.1 Deletion

Online Study of People Who Have Genetic Changes and Features of Autism: Simons Searchlight

RECRUITING
NCT01238250Simons SearchlightStarted 2010-10
Dravet Syndrome

A Clinical Study to Evaluate the Safety and Efficacy of ETX101 in Infants and Children With SCN1A-Positive Dravet Syndrome

RECRUITING
NCT05419492Phase PHASE1, PHASE2Encoded TherapeuticsStarted 2024-05-14
ETX101
Dravet SyndromeEpilepsy

Neurodevelopmental Impact of Epilepsy on Autonomic Function in Dravet Syndrome

ACTIVE NOT RECRUITING
NCT05472389Phase NAHospices Civils de LyonStarted 2022-10-14
Video-electroencephalographyBlood Samples
Dravet Syndrome

A Clinical Study to Evaluate the Safety and Efficacy of ETX101, an AAV9-Delivered Gene Therapy in Children With SCN1A-positive Dravet Syndrome (Australia Only)

ACTIVE NOT RECRUITING
NCT06112275Phase PHASE1, PHASE2Encoded TherapeuticsStarted 2024-02-28
ETX101
Dravet Syndrome

A Clinical Study to Evaluate the Safety and Efficacy of ETX101, an AAV9-Delivered Gene Therapy in Children With SCN1A-positive Dravet Syndrome

ACTIVE NOT RECRUITING
NCT06283212Phase PHASE1, PHASE2Encoded TherapeuticsStarted 2024-05-09
ETX101
EpilepsyDravet SyndromeDrug Resistant Epilepsy

A PET-MRI Study of Serotoninergic Brainstem Pathway in Patients With Dravet Syndrome

RECRUITING
NCT07013331Phase NAHospices Civils de LyonStarted 2026-05-04
[18F]MPPF PET-MRI
Dravet Syndrome

EXploring novEl Molecular Determinants of DRAvet Syndrome Phenotype Heterogeneity

ENROLLING BY INVITATION
NCT06371794Phase NAFondazione Policlinico Universitario Agostino Gemelli IRCCSStarted 2023-07-06
skin punch biopsy
Clinical Literature
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Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗