SBK1

Chr 16

SH3 domain binding kinase 1

Also known as: SBK

The protein is predicted to function as a serine/threonine kinase involved in chromatin remodeling and may participate in signal transduction pathways controlling brain development. Currently, no established Mendelian diseases have been definitively associated with SBK1 mutations in clinical practice. The gene shows moderate constraint against loss-of-function variants, suggesting potential intolerance to complete protein loss.

OMIMResearchSummary from RefSeq, UniProt
GOFmechanismLOEUF 0.70
Clinical SummarySBK1
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.22) despite low pLI — interpret in context.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.70LOEUF
pLI 0.368
Z-score 2.16
OE 0.22 (0.090.70)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
2.94Z-score
OE missense 0.47 (0.410.55)
117 obs / 246.9 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.22 (0.090.70)
00.351.4
Missense OE0.47 (0.410.55)
00.61.4
Synonymous OE0.81
01.21.6
LoF obs/exp: 2 / 9.0Missense obs/exp: 117 / 246.9Syn Z: 1.62
DN
0.5379th %ile
GOF
0.81top 10%
LOF
0.4726th %ile

The highest-scoring mechanism for this gene is gain-of-function.

GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

SBK1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗