SBE2

Chr 7AD

SHH brain enhancer 2

This region contains a brain enhancer that likely regulates expression of the sonic hedgehog (SHH) gene, located approximately 460 kb downstream. A mutation in this sequence disrupts binding by homeobox protein SIX3 and causes holoprosencephaly (HPE). [provided by RefSeq, Sep 2015]

Primary Disease Associations & Inheritance

Holoprosencephaly 2MIM #157170
AD
SchizencephalyMIM #269160
45
ClinVar variants
43
Pathogenic / LP
pLI score
0
Active trials
Clinical SummarySBE2
📋
ClinVar Variants
43 Pathogenic / Likely Pathogenic· 2 VUS of 45 total submissions
Some data sources returned errors (2)

ensembl: Error: Ensembl fetch failed: 400 for https://rest.ensembl.org/lookup/symbol/homo_sapiens/SBE2?content-type=application/json&expand=1

gnomad: Error: Gene not found

Population Genetics & Constraint

Constraint data not available from gnomAD.

ClinVar Variant Classifications

45 submitted variants in ClinVar

Classification Summary

Pathogenic39
Likely Pathogenic4
VUS2
39
Pathogenic
4
Likely Pathogenic
2
VUS

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
39
Likely Pathogenic
4
VUS
2
Likely Benign
0
Benign
0
Total45

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

SBE2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

OMIM — Genotype-Phenotype Relationships

1 OMIM entry

SIX HOMEOBOX 3; SIX3
MIM #603714 · *

Holoprosencephaly 2

MIM #157170

Molecular basis of disorder known

Autosomal dominant

Schizencephaly

MIM #269160

Molecular basis of disorder known

Clinical Literature
Landmark / reviewRecent case evidence
Key Publications
Landmark & review papers · by relevance
PubMed
Top 10 resultsSearch PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →