SAP30

Chr 4

Sin3A associated protein 30

The protein is a component of the Sin3-histone deacetylase complex that deacetylates core histone octamers and recruits this complex to specific corepressor complexes for transcriptional repression. Mutations cause autosomal dominant intellectual disability with developmental delay and behavioral abnormalities. The gene shows moderate constraint against loss-of-function variants, suggesting some intolerance to complete protein loss.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
8
Pubs (1 yr)
62
P/LP submissions
0%
P/LP missense
0.76
LOEUF
LOF
Mechanism· predicted
Clinical SummarySAP30
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.24) despite low pLI — interpret in context.
📋
ClinVar Variants
62 unique Pathogenic / Likely Pathogenic· 30 VUS of 96 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.76LOEUF
pLI 0.310
Z-score 2.02
OE 0.24 (0.100.76)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.89Z-score
OE missense 0.75 (0.630.91)
77 obs / 102.2 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.24 (0.100.76)
00.351.4
Missense OE0.75 (0.630.91)
00.61.4
Synonymous OE1.01
01.21.6
LoF obs/exp: 2 / 8.3Missense obs/exp: 77 / 102.2Syn Z: -0.05
DN
0.4488th %ile
GOF
0.4085th %ile
LOF
0.68top 25%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

96 submitted variants in ClinVar

Classification Summary

Pathogenic59
Likely Pathogenic3
VUS30
59
Pathogenic
3
Likely Pathogenic
30
VUS

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
59
0
59
Likely Pathogenic
0
0
3
0
3
VUS
0
24
6
0
30
Likely Benign
0
0
0
0
0
Benign
0
0
0
0
0
Total02468092

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

SAP30 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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