SAMD11

Chr 1

sterile alpha motif domain containing 11

Also known as: MRS

SAMD11 encodes a component of a Polycomb repressive complex (PRC1) that silences non-rod gene expression to establish rod photoreceptor cell identity and function during retinal development. Mutations cause autosomal recessive retinal dystrophy with early childhood onset, leading to progressive vision loss. The gene shows minimal constraint against loss-of-function variants in the general population.

Summary from RefSeq, UniProt
Research Assistant →

Primary Disease Associations & Inheritance

UniProtRetinitis pigmentosa
0
Active trials
1
Pubs (1 yr)
8
P/LP submissions
0%
P/LP missense
1.28
LOEUF
LOF
Mechanism· G2P
Clinical SummarySAMD11
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
8 unique Pathogenic / Likely Pathogenic· 166 VUS of 400 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.28LOEUF
pLI 0.000
Z-score 0.47
OE 0.90 (0.641.28)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-3.44Z-score
OE missense 1.51 (1.411.62)
546 obs / 362.0 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.90 (0.641.28)
00.351.4
Missense OE1.51 (1.411.62)
00.61.4
Synonymous OE1.70
01.21.6
LoF obs/exp: 22 / 24.5Missense obs/exp: 546 / 362.0Syn Z: -6.92

ClinVar Variant Classifications

400 submitted variants in ClinVar

Classification Summary

Pathogenic8
VUS166
Likely Benign211
Benign5
Conflicting1
8
Pathogenic
166
VUS
211
Likely Benign
5
Benign
1
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
8
0
8
Likely Pathogenic
0
0
0
0
0
VUS
10
140
16
0
166
Likely Benign
0
4
82
125
211
Benign
0
0
3
2
5
Conflicting
1
Total10144109127391

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

SAMD11 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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