RTL4

Chr X

retrotransposon Gag like 4

Also known as: Mar4, Mart4, SIRH1, SIRH11, ZCCHC16

The RTL4 protein binds nucleic acids and zinc ions and is involved in cognitive function in the brain, possibly via the noradrenergic system. Mutations cause intellectual disability with severe speech delay and mild dysmorphism, inherited in an autosomal recessive pattern. This gene shows low constraint to loss-of-function variation, consistent with the recessive inheritance pattern observed clinically.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 1.79
Clinical SummaryRTL4
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.79LOEUF
pLI 0.000
Z-score -0.20
OE 1.08 (0.631.79)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.53Z-score
OE missense 1.14 (0.991.32)
130 obs / 114.1 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.08 (0.631.79)
00.351.4
Missense OE1.14 (0.991.32)
00.61.4
Synonymous OE0.96
01.21.6
LoF obs/exp: 8 / 7.4Missense obs/exp: 130 / 114.1Syn Z: 0.21
DN
0.81top 10%
GOF
0.5857th %ile
LOF
0.2288th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

RTL4 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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